Search GLEAM-DB / CoGenEx-PM3

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Recognized gene
KCNQ1
Normalized c.HGVS
c.-3G>A, c.1070A>G, c.1132G>A, c.1190G>A, c.1196C>G and 44 more
Normalized p.HGVS
p.(=), p.(Ala194Pro), p.(Ala287Glu), p.(Ala287Ser), p.(Ala287Thr) and 44 more
Matching records
430
PM3-positive records
18

Results are ordered by PM3-relevant evidence first. Reviewed source only indicates whether main text, supplementary material, or both were reviewed; it is not the evidence conclusion.

Download current query results as TSV
Gene Variant Evidence PM3 context Publication Reviewed source Actions
KCNQ1 NM_000218.3:c.574C>T Phase-confirmed PM3 evidence
High confidence
Confirmed in trans with c.1032G>A; Ala344Alasp; p.Ala344Alasp
context: Confirmed in trans
22629021
Genotype-phenotype analysis of three Chinese families with Jervell and Lange-Nielsen syndrome.
Journal of cardiovascular disease research, 2012
Main article
Open
KCNQ1 NM_000218.3:c.574C>T Phase-unconfirmed biallelic evidence
High confidence
Homozygous for query variant
context: Homozygous evidence
41768584
Case Report Series: Genetic and clinical characterization of long QT syndrome in admixed Ecuadorian patients and its implications for sudden cardiac death risk.
Frontiers in cardiovascular medicine, 2026
Main article
Open
KCNQ1 NM_000218.3:c.1831G>A Phase-unconfirmed biallelic evidence
High confidence
Possible compound heterozygous with c.546C>A; p.S182R
context: Compound heterozygous candidate
41147441
Molecular mechanisms of function deficiencies in KCNQ1 variants associated with Jervell and Lange-Nielsen syndrome.
Channels (Austin, Tex.), 2025
Main article
Open
KCNQ1 NM_000218.3:c.217C>A Phase-unconfirmed biallelic evidence
High confidence
Possible compound heterozygous with c.328G>A; p.Val110Ile
context: Compound heterozygous candidate
38756210
Cardiac arrhythmia and epilepsy genetic variants in sudden unexpected death in epilepsy.
Frontiers in neurology, 2024
Main article
Open
KCNQ1 NM_000218.3:c.590C>T Phase-unconfirmed biallelic evidence
High confidence
Possible compound heterozygous with K196T
context: Compound heterozygous candidate
36339618
Evolutionary coupling analysis guides identification of mistrafficking-sensitive variants in cardiac K(+) channels: Validation with hERG.
Frontiers in pharmacology, 2022
Supplementary material
Open
KCNQ1 NM_000218.3:c.31G>A Phase-unconfirmed biallelic evidence
High confidence
Potential PM3 evidence identified; genotype context not structured
context: PM3 evidence context not structured
33614747
Territory-Wide Chinese Cohort of Long QT Syndrome: Random Survival Forest and Cox Analyses.
Frontiers in cardiovascular medicine, 2021
Main article
Open
KCNQ1 NM_000218.3:c.328G>A Phase-unconfirmed biallelic evidence
Needs review
Possible compound heterozygous with H105L
context: Compound heterozygous candidate
30828412
Protein structure aids predicting functional perturbation of missense variants in SCN5A and KCNQ1.
Computational and structural biotechnology journal, 2019
Supplementary material
Open
KCNQ1 NM_000218.3:c.590C>T Phase-unconfirmed biallelic evidence
Needs review
Possible compound heterozygous with I227L; P197S; R109L; +4 more
context: Compound heterozygous candidate
30828412
Protein structure aids predicting functional perturbation of missense variants in SCN5A and KCNQ1.
Computational and structural biotechnology journal, 2019
Supplementary material
Open
KCNQ1 NM_000218.3:c.217C>A Phase-unconfirmed biallelic evidence
High confidence
Potential PM3 evidence identified; genotype context not structured
context: Compound heterozygous candidate
28588847
A case of long QT syndrome: challenges on a bumpy road.
Clinical case reports, 2017
Main article
Open
KCNQ1 NM_000218.3:c.1876G>A Phase-unconfirmed biallelic evidence
High confidence
Homozygous for query variant
context: Homozygous evidence
28316956
Sudden infant death syndrome due to long QT syndrome: a brief review of the genetic substrate and prevalence.
Journal of biological research (Thessalonike, Greece), 2017
Main article
Open
KCNQ1 NM_000218.3:c.1831G>A Phase-unconfirmed biallelic evidence
High confidence
Possible compound heterozygous with c.546C > A; p. S182R
context: Compound heterozygous candidate
27917693
Identification of KCNQ1 compound heterozygous mutations in three Chinese families with Jervell and Lange-Nielsen Syndrome.
Acta oto-laryngologica, 2017
Main article
Open
KCNQ1 NM_000218.3:c.1343C>A Phase-unconfirmed biallelic evidence
Needs review
Possible compound heterozygous with second mutation with abnormal electrophysiological properties; second mutation within the transmembrane region
context: Compound heterozygous candidate
25854863
Enhancing the Predictive Power of Mutations in the C-Terminus of the KCNQ1-Encoded Kv7.1 Voltage-Gated Potassium Channel.
Journal of cardiovascular translational research, 2015
Main article
Open
KCNQ1 NM_000218.3:c.1343C>T Phase-unconfirmed biallelic evidence
Needs review
Possible compound heterozygous with second mutation with abnormal electrophysiological properties; second mutation within the transmembrane region
context: Compound heterozygous candidate
25854863
Enhancing the Predictive Power of Mutations in the C-Terminus of the KCNQ1-Encoded Kv7.1 Voltage-Gated Potassium Channel.
Journal of cardiovascular translational research, 2015
Main article
Open
KCNQ1 NM_000218.3:c.1351C>T Phase-unconfirmed biallelic evidence
Needs review
Possible compound heterozygous with second mutation that was either within the transmembrane region or previously shown to have an abnormal electrophysiological properties
context: Compound heterozygous candidate
25854863
Enhancing the Predictive Power of Mutations in the C-Terminus of the KCNQ1-Encoded Kv7.1 Voltage-Gated Potassium Channel.
Journal of cardiovascular translational research, 2015
Main article
Open
KCNQ1 NM_000218.3:c.1201C>T Phase-unconfirmed biallelic evidence
High confidence
Possible compound heterozygous with c.1_2insA; c.G1520A; p.M1fs; +1 more
context: Compound heterozygous candidate
23396983
Genetic complexity in hypertrophic cardiomyopathy revealed by high-throughput sequencing.
Journal of medical genetics, 2013
Supplementary material
Open
KCNQ1 NM_000218.3:c.1343C>T Phase-unconfirmed biallelic evidence
Needs review
Possible compound heterozygous with P320S
context: Compound heterozygous candidate
23392653
Prevalence and potential genetic determinants of sensorineural deafness in KCNQ1 homozygosity and compound heterozygosity.
Circulation. Cardiovascular genetics, 2013
Main article
Open
KCNQ1 NM_000218.3:c.958C>T Phase-unconfirmed biallelic evidence
Needs review
Possible compound heterozygous with P448L
context: Compound heterozygous candidate
23392653
Prevalence and potential genetic determinants of sensorineural deafness in KCNQ1 homozygosity and compound heterozygosity.
Circulation. Cardiovascular genetics, 2013
Main article
Open
KCNQ1 NM_000218.3:c.217C>A Phase-unconfirmed biallelic evidence
High confidence
Potential PM3 evidence identified; genotype context not structured
context: Compound heterozygous candidate
23098067
Founder mutations characterise the mutation panorama in 200 Swedish index cases referred for Long QT syndrome genetic testing.
BMC cardiovascular disorders, 2012
Main article
Open
KCNQ1 NM_000218.3:c.1520G>A Other Patient-Level Evidence
High confidence
Patient-level evidence found, not PM3
context: Other patient-level evidence
40617375
Sudden cardiac death in young: A cardiac-focused autopsy and molecular study to identify the cause.
Indian heart journal, 2025
Main article
Open
KCNQ1 NM_000218.3:c.397G>A Other Patient-Level Evidence
Needs review
Patient-level evidence found, not PM3
context: Other patient-level evidence
32797034
A computational model of induced pluripotent stem-cell derived cardiomyocytes for high throughput risk stratification of KCNQ1 genetic variants.
PLoS computational biology, 2020
Main article
Open