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Recognized gene
CEP290
Normalized c.HGVS
c.1054G>T, c.1150A>G, c.1175T>G, c.2029C>T, c.2090C>T and 45 more
Normalized p.HGVS
p.(Ala1260Thr), p.(Ala1432Thr), p.(Ala352Ser), p.(Ala697Val), p.(Arg1072Trp) and 43 more
Matching records
200
PM3-positive records
15

Results are ordered by PM3-relevant evidence first. Reviewed source only indicates whether main text, supplementary material, or both were reviewed; it is not the evidence conclusion.

Download current query results as TSV
Gene Variant Evidence PM3 context Publication Reviewed source Actions
CEP290 NM_025114.4:c.5932C>G Phase-unconfirmed biallelic evidence
Needs review
Possible compound heterozygous with c.1075 G>T; p.Glu359Ter
context: Compound heterozygous candidate
37766766
A Report on Children with CEP290 Mutation, Vision Loss, and Developmental Delay.
Beyoglu eye journal, 2023
Main article
Open
CEP290 NM_025114.4:c.31A>G Phase-unconfirmed biallelic evidence
High confidence
Possible compound heterozygous with c.2848dup; p.Gln950ProfsTer6; dup
context: Compound heterozygous candidate
35764379
Uncovering the burden of hidden ciliopathies in the 100 000 Genomes Project: a reverse phenotyping approach.
Journal of medical genetics, 2022
Supplementary material
Open
CEP290 NM_025114.4:c.5284C>T Phase-unconfirmed biallelic evidence
High confidence
Homozygous for query variant
context: Homozygous evidence
35764379
Uncovering the burden of hidden ciliopathies in the 100 000 Genomes Project: a reverse phenotyping approach.
Journal of medical genetics, 2022
Main article
Open
CEP290 NM_025114.4:c.6134C>T Phase-unconfirmed biallelic evidence
High confidence
Possible compound heterozygous with c.7394_7395del; p.Glu2465ValfsTer2; fsTer2
context: Compound heterozygous candidate
35123515
Utility of next-generation sequencing in genetic testing and counseling of disorders involving the musculoskeletal system-trends observed from a single genetic unit.
Journal of orthopaedic surgery and research, 2022
Main article
Open
CEP290 NM_025114.4:c.5932C>G Phase-unconfirmed biallelic evidence
Needs review
Homozygous for query variant
context: Homozygous evidence
35019165
Novel variants underlying autosomal recessive neurodevelopmental disorders with intellectual disability in Iranian consanguineous families.
Journal of clinical laboratory analysis, 2022
Main article
Open
CEP290 NM_025114.4:c.2252G>A Phase-unconfirmed biallelic evidence
High confidence
Possible compound heterozygous with c.1298A>G; p.(Asp433Gly)
context: Compound heterozygous candidate
34196655
Spectrum of Disease Severity in Nonsyndromic Patients With Mutations in the CEP290 Gene: A Multicentric Longitudinal Study.
Investigative ophthalmology & visual science, 2021
Main article
Open
CEP290 NM_025114.4:c.2723G>A Phase-unconfirmed biallelic evidence
High confidence
Possible compound heterozygous with c.5493del; p.(Ala1832Profs*19)
context: Compound heterozygous candidate
34196655
Spectrum of Disease Severity in Nonsyndromic Patients With Mutations in the CEP290 Gene: A Multicentric Longitudinal Study.
Investigative ophthalmology & visual science, 2021
Main article
Open
CEP290 NM_025114.4:c.2423A>G Phase-unconfirmed biallelic evidence
High confidence
Homozygous for query variant
context: Homozygous evidence
33921431
Towards a Change in the Diagnostic Algorithm of Autism Spectrum Disorders: Evidence Supporting Whole Exome Sequencing as a First-Tier Test.
Genes, 2021
Main article
Open
CEP290 NM_025114.4:c.2615C>T Phase-unconfirmed biallelic evidence
High confidence
Possible compound heterozygous with p.K140R
context: Compound heterozygous candidate
31488071
Screening of 31 genes involved in monogenic forms of obesity in 23 Pakistani probands with early-onset childhood obesity: a case report.
BMC medical genetics, 2019
Supplementary material
Open
CEP290 NM_025114.4:c.3132G>T Phase-unconfirmed biallelic evidence
High confidence
Possible compound heterozygous with c.1775G>T; c.452G>A; R151Q; +1 more
context: Compound heterozygous candidate
29604063
Somatic POLE exonuclease domain mutations are early events in sporadic endometrial and colorectal carcinogenesis, determining driver mutational landscape, clonal neoantigen burden and immune response.
The Journal of pathology, 2018
Supplementary material
Open
CEP290 NM_025114.4:c.3251G>A Phase-unconfirmed biallelic evidence
High confidence
Possible compound heterozygous with c.193G>T; E65*
context: Compound heterozygous candidate
29604063
Somatic POLE exonuclease domain mutations are early events in sporadic endometrial and colorectal carcinogenesis, determining driver mutational landscape, clonal neoantigen burden and immune response.
The Journal of pathology, 2018
Supplementary material
Open
CEP290 NM_025114.4:c.4150C>T Phase-unconfirmed biallelic evidence
High confidence
Homozygous for query variant
context: Homozygous evidence
28600779
The landscape of genetic diseases in Saudi Arabia based on the first 1000 diagnostic panels and exomes.
Human genetics, 2017
Supplementary material
Open
CEP290 NM_025114.4:c.2929A>G Phase-unconfirmed biallelic evidence
High confidence
Possible compound heterozygous with c.4028delA; p.K1343fs; fs
context: Compound heterozygous candidate
28157192
Unravelling the genetic basis of simplex Retinitis Pigmentosa cases.
Scientific reports, 2017
Main article
Open
CEP290 NM_025114.4:c.3758G>A Phase-unconfirmed biallelic evidence
High confidence
Possible compound heterozygous with c.2578G>T; c.5254C>T; p.Arg1752Trp; +1 more
context: Compound heterozygous candidate
24265693
Increasing the yield in targeted next-generation sequencing by implicating CNV analysis, non-coding exons and the overall variant load: the example of retinal dystrophies.
PloS one, 2013
Main article
Open
CEP290 NM_025114.4:c.5226+5_5226+8del Phase-unconfirmed biallelic evidence
Not assessed
Possible compound heterozygous with c.95T>C; p.L32S
context: Compound heterozygous candidate
23559409
Identification of 99 novel mutations in a worldwide cohort of 1,056 patients with a nephronophthisis-related ciliopathy.
Human genetics, 2013
Main article
Open
CEP290 NM_025114.4:c.6628C>T Other Patient-Level Evidence
High confidence
Patient-level evidence found, not PM3
context: Other patient-level evidence
40565534
Investigating the Role of B9D1 in Meckel-Gruber Syndrome: A Case Report and Comprehensive Literature Review.
Genes, 2025
Main article
Open
CEP290 NM_025114.4:c.4577A>T Other Patient-Level Evidence
High confidence
Patient-level evidence found, not PM3
context: Other patient-level evidence
36369640
Molecular background of Leber congenital amaurosis in a Polish cohort of patients-novel variants discovered by NGS.
Journal of applied genetics, 2023
Main article
Open
CEP290 NM_025114.4:c.6320A>G Other Patient-Level Evidence
High confidence
Patient-level evidence found, not PM3
context: Other patient-level evidence
29974258
Clinical and genetic analyses of a Dutch cohort of 40 patients with a nephronophthisis-related ciliopathy.
Pediatric nephrology (Berlin, Germany), 2018
Main article
Open
CEP290 NM_025114.4:c.2320G>C Other Patient-Level Evidence
High confidence
Patient-level evidence found, not PM3
context: Other patient-level evidence
28152038
Exome sequencing covers >98% of mutations identified on targeted next generation sequencing panels.
PloS one, 2017
Supplementary material
Open
CEP290 NM_025114.4:c.3593C>T Other Patient-Level Evidence
High confidence
Patient-level evidence found, not PM3
context: Other patient-level evidence
26496393
Dependable and Efficient Clinical Molecular Diagnosis of Chinese RP Patient with Targeted Exon Sequencing.
PloS one, 2015
Supplementary material
Open